Author(s)

Hiromitsu Yamamoto¹, Ken-ichiro Murakami², Mariko Kawai^1,3, Hitoshi Nagatsuka⁴, Kazuhisa Bessho¹

¹Department of Oral and Maxillofacial Surgery, Graduate School of Medicine, Kyoto University, Kyoto, Japan.
²Department of Oral and Maxillofacial Surgery, Ako City Hospital, Ako, Japan.
³Department of Pharmacology, Osaka Dental University, Osaka, Japan.
⁴Department of Oral Pathology and Medicine, Graduate School of Medicine and Dentistry, Okayama University, Okayama, Japan.

Vascular malformations occur most frequently in the maxillofacial and oral regions. Although many cases of vascular malformations with phlebolithiasis have been reported, only few reports have documented cases of thrombosis formation. We report a rare case of a vascular malformation with multiple thromboses in the left buccal region. A 28-year-old woman had a painless swelling in the left cheek when she consulted our hospital. T1-weighted magnetic resonance imaging revealed a low-signal lesion, having the same intensity as the muscle, in the left buccal region, and T2-weighted imaging revealed a high-signal lesion. Additionally, three tuberous tumours were noted in this lesion showing both a light high signal on T1-weighted imaging and a low signal on T2-weighted imaging. Based on these imaging findings, as well as clinical and pathological findings, the patient was diagnosed with multiple vascular malformations in the left midfacial region. The three tuberous tumours showed necrotic tissue in the central area, which was formed by calcified and concentric fibrous tissue, and vascularization. Because tumorous lesion and typical vascular structure by the Elastica Van Gieson staining were not observed, these tumours were seemed that fibrin thrombus in this lesion formed the organized tissue.

Vascular Malformation, Thrombosis, Tuberous Tumour, Buccal Region, EVG Staining

Yamamoto, H. , Murakami, K. , Kawai, M. , Nagatsuka, H. and Bessho, K. (2017) Vascular Malformation with Multiple Organized Thromboses in Buccal Region. Open Journal of Stomatology, 7, 388-396. doi: 10.4236/ojst.2017.79033.